{"id":"https://openalex.org/W7225424080","doi":"https://doi.org/10.1002/ccr3.73883","title":"Hereditary Hemorrhagic Telangiectasia of the Tongue: A Rare Case Report","display_name":"Hereditary Hemorrhagic Telangiectasia of the Tongue: A Rare Case Report","publication_year":2026,"publication_date":"2026-11-01","ids":{"openalex":"https://openalex.org/W7225424080","doi":"https://doi.org/10.1002/ccr3.73883","pmid":"https://pubmed.ncbi.nlm.nih.gov/42997498","pmcid":"https://www.ncbi.nlm.nih.gov/pmc/articles/13741848"},"language":"en","primary_location":{"id":"doi:10.1002/ccr3.73883","doi":"https://doi.org/10.1002/ccr3.73883","is_oa":true,"landing_page_url":"https://doi.org/10.1002/ccr3.73883","pdf_url":"https://onlinelibrary.wiley.com/doi/pdfdirect/10.1002/ccr3.73883","source":{"id":"https://openalex.org/S2737168579","display_name":"Clinical Case Reports","issn_l":"2050-0904","issn":["2050-0904"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["cwts-core","doaj","norway-1","poland-20","vabb-shw"],"host_organization":"https://openalex.org/P4310320595","host_organization_name":"Wiley","host_organization_lineage":["https://openalex.org/P4310320595"],"host_organization_lineage_names":["Wiley"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Clinical Case Reports","raw_type":"journal-article"},"volume":null,"type":"article","is_traditional":true,"indexed_in":["crossref","doaj","pubmed"],"open_access":{"is_oa":true,"oa_status":"gold","oa_url":"https://onlinelibrary.wiley.com/doi/pdfdirect/10.1002/ccr3.73883","any_repository_has_fulltext":true},"authorships":[{"author_position":"first","author":{"id":"https://openalex.org/A5056906400","display_name":"Saede Atarbashi\u2010Moghadam","orcid":"https://orcid.org/0000-0002-1731-2786","observed_orcids":["https://orcid.org/0000-0002-1731-2786"]},"institutions":[{"id":"https://openalex.org/I48379061","display_name":"Shahid Beheshti University","ror":"https://ror.org/0091vmj44","country_code":"IR","type":"education","lineage":["https://openalex.org/I48379061"]},{"id":"https://openalex.org/I58048189","display_name":"Shahid Beheshti University of Medical Sciences","ror":"https://ror.org/034m2b326","country_code":"IR","type":"education","lineage":["https://openalex.org/I58048189"]}],"countries":["IR"],"is_corresponding":false,"raw_author_name":"Saede Atarbashi\u2010Moghadam","raw_affiliation_strings":["Department of Oral and Maxillofacial Pathology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran"],"raw_orcid":"https://orcid.org/0000-0002-1731-2786","affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial Pathology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran","institution_ids":["https://openalex.org/I48379061","https://openalex.org/I58048189"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5101443836","display_name":"Ali Lotfi","orcid":"https://orcid.org/0000-0003-0774-841X","observed_orcids":["https://orcid.org/0000-0003-0774-841X"]},"institutions":[{"id":"https://openalex.org/I48379061","display_name":"Shahid Beheshti University","ror":"https://ror.org/0091vmj44","country_code":"IR","type":"education","lineage":["https://openalex.org/I48379061"]},{"id":"https://openalex.org/I58048189","display_name":"Shahid Beheshti University of Medical Sciences","ror":"https://ror.org/034m2b326","country_code":"IR","type":"education","lineage":["https://openalex.org/I58048189"]}],"countries":["IR"],"is_corresponding":false,"raw_author_name":"Ali Lotfi","raw_affiliation_strings":["Department of Oral and Maxillofacial Pathology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran"],"raw_orcid":"https://orcid.org/0000-0003-0774-841X","affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial Pathology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran","institution_ids":["https://openalex.org/I48379061","https://openalex.org/I58048189"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5090935769","display_name":"Fazele Atarbashi\u2010Moghadam","orcid":"https://orcid.org/0000-0002-3499-2250","observed_orcids":["https://orcid.org/0000-0002-3499-2250"]},"institutions":[{"id":"https://openalex.org/I48379061","display_name":"Shahid Beheshti University","ror":"https://ror.org/0091vmj44","country_code":"IR","type":"education","lineage":["https://openalex.org/I48379061"]},{"id":"https://openalex.org/I58048189","display_name":"Shahid Beheshti University of Medical Sciences","ror":"https://ror.org/034m2b326","country_code":"IR","type":"education","lineage":["https://openalex.org/I58048189"]}],"countries":["IR"],"is_corresponding":false,"raw_author_name":"Fazele Atarbashi\u2010Moghadam","raw_affiliation_strings":["Department of Periodontology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran"],"raw_orcid":"https://orcid.org/0000-0002-3499-2250","affiliations":[{"raw_affiliation_string":"Department of Periodontology School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran","institution_ids":["https://openalex.org/I48379061","https://openalex.org/I58048189"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5077559649","display_name":"Mostafa Mohamed Ragheb Alam","orcid":"https://orcid.org/0000-0003-3827-9708","observed_orcids":["https://orcid.org/0000-0003-3827-9708"]},"institutions":[{"id":"https://openalex.org/I48379061","display_name":"Shahid Beheshti University","ror":"https://ror.org/0091vmj44","country_code":"IR","type":"education","lineage":["https://openalex.org/I48379061"]},{"id":"https://openalex.org/I58048189","display_name":"Shahid Beheshti University of Medical Sciences","ror":"https://ror.org/034m2b326","country_code":"IR","type":"education","lineage":["https://openalex.org/I58048189"]}],"countries":["IR"],"is_corresponding":false,"raw_author_name":"Mostafa Alam","raw_affiliation_strings":["Department of Oral and Maxillofacial Surgery School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran"],"raw_orcid":"https://orcid.org/0000-0003-3827-9708","affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial Surgery School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran","institution_ids":["https://openalex.org/I48379061","https://openalex.org/I58048189"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5063061875","display_name":"Milad Baseri","orcid":"https://orcid.org/0000-0001-8531-8699","observed_orcids":["https://orcid.org/0000-0001-8531-8699"]},"institutions":[{"id":"https://openalex.org/I48379061","display_name":"Shahid Beheshti University","ror":"https://ror.org/0091vmj44","country_code":"IR","type":"education","lineage":["https://openalex.org/I48379061"]},{"id":"https://openalex.org/I58048189","display_name":"Shahid Beheshti University of Medical Sciences","ror":"https://ror.org/034m2b326","country_code":"IR","type":"education","lineage":["https://openalex.org/I58048189"]}],"countries":["IR"],"is_corresponding":false,"raw_author_name":"Milad Baseri","raw_affiliation_strings":["Department of Oral and Maxillofacial Surgery School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran"],"raw_orcid":"https://orcid.org/0000-0001-8531-8699","affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial Surgery School of Dentistry, Shahid Beheshti University of Medical Sciences  Tehran Iran","institution_ids":["https://openalex.org/I48379061","https://openalex.org/I58048189"]}]},{"author_position":"last","author":{"id":"https://openalex.org/A5120513147","display_name":"Mohammadreza Kashefi Baher","orcid":"https://orcid.org/0009-0009-7740-025X","observed_orcids":["https://orcid.org/0009-0009-7740-025X"]},"institutions":[{"id":"https://openalex.org/I4405263198","display_name":"Chamran Hospital","ror":"https://ror.org/03snf8k67","country_code":"IR","type":"healthcare","lineage":["https://openalex.org/I4405263198"]}],"countries":["IR"],"is_corresponding":true,"raw_author_name":"Mohammadreza Kashefi Baher","raw_affiliation_strings":["Health Research Center, Chamran Hospital  Tehran Iran"],"raw_orcid":"https://orcid.org/0009-0009-7740-025X","affiliations":[{"raw_affiliation_string":"Health Research Center, Chamran Hospital  Tehran Iran","institution_ids":["https://openalex.org/I4405263198"]}]}],"institutions":[],"countries_distinct_count":1,"institutions_distinct_count":3,"corresponding_author_ids":["https://openalex.org/A5120513147"],"corresponding_institution_ids":["https://openalex.org/I4405263198"],"apc_list":{"value":1820,"currency":"USD","value_usd":1820},"apc_paid":{"value":1820,"currency":"USD","value_usd":1820},"fwci":0.0,"has_fulltext":true,"cited_by_count":0,"citation_normalized_percentile":{"value":0.88459319,"is_in_top_1_percent":false,"is_in_top_10_percent":false},"cited_by_percentile_year":null,"biblio":{"volume":"14","issue":"11","first_page":"e73883","last_page":"e73883"},"is_retracted":false,"is_paratext":false,"is_xpac":false,"primary_topic":{"id":"https://openalex.org/T12199","display_name":"Vascular Anomalies and Treatments","score":0.9994999766349792,"subfield":{"id":"https://openalex.org/subfields/2716","display_name":"Genetics (clinical)"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},"topics":[{"id":"https://openalex.org/T12199","display_name":"Vascular Anomalies and Treatments","score":0.9994999766349792,"subfield":{"id":"https://openalex.org/subfields/2716","display_name":"Genetics (clinical)"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},{"id":"https://openalex.org/T10980","display_name":"Vascular Malformations and Hemangiomas","score":0.0,"subfield":{"id":"https://openalex.org/subfields/2746","display_name":"Surgery"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},{"id":"https://openalex.org/T11452","display_name":"Oral Health Pathology and Treatment","score":0.0,"subfield":{"id":"https://openalex.org/subfields/3500","display_name":"General Dentistry"},"field":{"id":"https://openalex.org/fields/35","display_name":"Dentistry"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}}],"keywords":[{"id":"https://openalex.org/keywords/hereditary-hemorrhagic-telangiectasia","display_name":"hereditary hemorrhagic telangiectasia","score":1.0},{"id":"https://openalex.org/keywords/tongue","display_name":"tongue","score":0.5860000252723694},{"id":"https://openalex.org/keywords/oral-mucosa","display_name":"oral mucosa","score":0.7020000219345093},{"id":"https://openalex.org/keywords/epistaxis","display_name":"epistaxis","score":0.7879999876022339},{"id":"https://openalex.org/keywords/iron-deficiency-anemia","display_name":"iron deficiency anemia","score":0.996999979019165},{"id":"https://openalex.org/keywords/antibiotic-prophylaxis","display_name":"antibiotic prophylaxis","score":0.8870000243186951},{"id":"https://openalex.org/keywords/amoxicillin","display_name":"amoxicillin","score":0.7369999885559082},{"id":"https://openalex.org/keywords/recurrence","display_name":"recurrence","score":0.34700000286102295},{"id":"https://openalex.org/keywords/vascular-malformations","display_name":"vascular malformations","score":0.550000011920929},{"id":"https://openalex.org/keywords/dental-management","display_name":"dental management","score":0.5360000133514404}],"concepts":[{"id":"https://openalex.org/C71924100","wikidata":"https://www.wikidata.org/wiki/Q11190","display_name":"Medicine","level":0,"score":0.982200026512146},{"id":"https://openalex.org/C2776330896","wikidata":"https://www.wikidata.org/wiki/Q1634800","display_name":"Telangiectasia","level":2,"score":0.8119999766349792},{"id":"https://openalex.org/C140530291","wikidata":"https://www.wikidata.org/wiki/Q1225063","display_name":"Dorsum","level":2,"score":0.4763000011444092},{"id":"https://openalex.org/C3020547009","wikidata":"https://www.wikidata.org/wiki/Q1070952","display_name":"Histopathological examination","level":2,"score":0.44449999928474426},{"id":"https://openalex.org/C141071460","wikidata":"https://www.wikidata.org/wiki/Q40821","display_name":"Surgery","level":1,"score":0.44119998812675476},{"id":"https://openalex.org/C527108885","wikidata":"https://www.wikidata.org/wiki/Q835153","display_name":"Physical examination","level":2,"score":0.4171999990940094},{"id":"https://openalex.org/C16005928","wikidata":"https://www.wikidata.org/wiki/Q171171","display_name":"Dermatology","level":1,"score":0.39239999651908875},{"id":"https://openalex.org/C2779443120","wikidata":"https://www.wikidata.org/wiki/Q650912","display_name":"Bacteremia","level":3,"score":0.3603000044822693},{"id":"https://openalex.org/C2779708577","wikidata":"https://www.wikidata.org/wiki/Q201928","display_name":"Amoxicillin","level":3,"score":0.3102000057697296},{"id":"https://openalex.org/C501593827","wikidata":"https://www.wikidata.org/wiki/Q12187","display_name":"Antibiotics","level":2,"score":0.3068999946117401},{"id":"https://openalex.org/C2777507709","wikidata":"https://www.wikidata.org/wiki/Q121576","display_name":"Vascular malformation","level":2,"score":0.2973000109195709},{"id":"https://openalex.org/C2910808297","wikidata":"https://www.wikidata.org/wiki/Q4774943","display_name":"Prophylactic antibiotic","level":4,"score":0.2971999943256378},{"id":"https://openalex.org/C2777466421","wikidata":"https://www.wikidata.org/wiki/Q1266890","display_name":"Vascular disease","level":2,"score":0.2939999997615814},{"id":"https://openalex.org/C206179267","wikidata":"https://www.wikidata.org/wiki/Q188952","display_name":"Medical history","level":2,"score":0.28029999136924744},{"id":"https://openalex.org/C2775958455","wikidata":"https://www.wikidata.org/wiki/Q7916449","display_name":"Vascular anomaly","level":2,"score":0.2775000035762787},{"id":"https://openalex.org/C3020230634","wikidata":"https://www.wikidata.org/wiki/Q12187","display_name":"Intravenous antibiotics","level":3,"score":0.2687999904155731},{"id":"https://openalex.org/C2778248108","wikidata":"https://www.wikidata.org/wiki/Q5445","display_name":"Anemia","level":2,"score":0.2581999897956848},{"id":"https://openalex.org/C142724271","wikidata":"https://www.wikidata.org/wiki/Q7208","display_name":"Pathology","level":1,"score":0.2572999894618988},{"id":"https://openalex.org/C2781179581","wikidata":"https://www.wikidata.org/wiki/Q2857712","display_name":"Family history","level":2,"score":0.2556999921798706},{"id":"https://openalex.org/C3020063470","wikidata":"https://www.wikidata.org/wiki/Q40821","display_name":"Surgical excision","level":2,"score":0.2542000114917755},{"id":"https://openalex.org/C81182388","wikidata":"https://www.wikidata.org/wiki/Q353963","display_name":"Complication","level":2,"score":0.25380000472068787}],"mesh":[],"locations_count":3,"locations":[{"id":"doi:10.1002/ccr3.73883","doi":"https://doi.org/10.1002/ccr3.73883","is_oa":true,"landing_page_url":"https://doi.org/10.1002/ccr3.73883","pdf_url":"https://onlinelibrary.wiley.com/doi/pdfdirect/10.1002/ccr3.73883","source":{"id":"https://openalex.org/S2737168579","display_name":"Clinical Case Reports","issn_l":"2050-0904","issn":["2050-0904"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["cwts-core","doaj","norway-1","poland-20","vabb-shw"],"host_organization":"https://openalex.org/P4310320595","host_organization_name":"Wiley","host_organization_lineage":["https://openalex.org/P4310320595"],"host_organization_lineage_names":["Wiley"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Clinical Case Reports","raw_type":"journal-article"},{"id":"pmid:42997498","doi":null,"is_oa":false,"landing_page_url":"https://pubmed.ncbi.nlm.nih.gov/42997498","pdf_url":null,"source":{"id":"https://openalex.org/S4306525036","display_name":"PubMed","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Clinical case reports","raw_type":"Journal Article"},{"id":"pmh:oai:pubmedcentral.nih.gov:13741848","doi":null,"is_oa":true,"landing_page_url":"https://pmc.ncbi.nlm.nih.gov/articles/PMC13741848/","pdf_url":null,"source":{"id":"https://openalex.org/S2764455111","display_name":"PubMed Central","issn_l":null,"issn":null,"is_oa":true,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Clin Case Rep","raw_type":"Text"}],"best_oa_location":{"id":"doi:10.1002/ccr3.73883","doi":"https://doi.org/10.1002/ccr3.73883","is_oa":true,"landing_page_url":"https://doi.org/10.1002/ccr3.73883","pdf_url":"https://onlinelibrary.wiley.com/doi/pdfdirect/10.1002/ccr3.73883","source":{"id":"https://openalex.org/S2737168579","display_name":"Clinical Case Reports","issn_l":"2050-0904","issn":["2050-0904"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["cwts-core","doaj","norway-1","poland-20","vabb-shw"],"host_organization":"https://openalex.org/P4310320595","host_organization_name":"Wiley","host_organization_lineage":["https://openalex.org/P4310320595"],"host_organization_lineage_names":["Wiley"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Clinical Case Reports","raw_type":"journal-article"},"sustainable_development_goals":[{"id":"https://metadata.un.org/sdg/3","display_name":"Good health and well-being","score":1.0}],"study_designs":[{"id":"https://openalex.org/study-designs/case-report","display_name":"Case Report"}],"awards":[],"funders":[],"has_content":{"pdf":true,"grobid_xml":true},"content_urls":{"pdf":"https://content.openalex.org/works/W7225424080.pdf","grobid_xml":"https://content.openalex.org/works/W7225424080.grobid-xml"},"referenced_works_count":5,"referenced_works":["https://openalex.org/W2066889223","https://openalex.org/W2117180856","https://openalex.org/W2171164791","https://openalex.org/W4283826815","https://openalex.org/W4385648787"],"related_works":["https://openalex.org/W2037561113","https://openalex.org/W2294147705","https://openalex.org/W2041617536","https://openalex.org/W2002869745","https://openalex.org/W2994672591","https://openalex.org/W4385648787","https://openalex.org/W4399446838","https://openalex.org/W1568654881","https://openalex.org/W1603695563","https://openalex.org/W3097649763"],"abstract_inverted_index":{"Hereditary":[0],"hemorrhagic":[1],"telangiectasia":[2],"(HHT)":[3],"is":[4],"a":[5,27,58,150],"rare":[6],"autosomal":[7],"dominant":[8],"vascular":[9,89],"disorder":[10],"that":[11],"may":[12],"involve":[13],"the":[14,40,44,94,97,121,130,136],"oral":[15,79,127],"mucosa,":[16],"providing":[17],"important":[18],"diagnostic":[19],"clues":[20],"for":[21,138],"dental":[22,140],"practitioners.":[23],"This":[24,118],"report":[25],"describes":[26],"54-year-old":[28],"female":[29],"presenting":[30],"with":[31,75,106,149,156],"recurrent":[32,49,124],"bleeding":[33,108],"from":[34],"multiple":[35],"red-purple":[36],"telangiectatic":[37],"papules":[38],"on":[39,65],"dorsal":[41],"surface":[42],"of":[43,78,99,126,132,152],"tongue.":[45],"Her":[46],"history":[47],"included":[48],"epistaxis,":[50],"severe":[51],"iron":[52],"deficiency":[53],"anemia,":[54],"pulmonary":[55,157],"involvement,":[56],"and":[57,123,135],"positive":[59],"family":[60],"history.":[61],"The":[62],"lesions":[63],"blanched":[64],"diascopy.":[66],"Symptomatic":[67],"management":[68],"using":[69],"electrocautery":[70],"excision":[71],"under":[72],"local":[73],"anesthesia":[74],"prophylactic":[76],"administration":[77],"amoxicillin":[80],"(2":[81],"g)":[82],"was":[83,104],"performed.":[84],"Histopathological":[85],"examination":[86],"demonstrated":[87],"thin-walled":[88],"spaces":[90],"containing":[91],"erythrocytes":[92],"beneath":[93],"epithelium,":[95],"confirming":[96],"diagnosis":[98],"HHT.":[100],"Although":[101],"postoperative":[102],"healing":[103],"uneventful":[105],"immediate":[107],"control,":[109],"recurrence":[110],"occurred":[111],"after":[112],"1":[113],"year,":[114],"necessitating":[115],"repeat":[116],"surgery.":[117],"case":[119],"highlights":[120],"progressive":[122],"nature":[125],"HHT":[128],"lesions,":[129],"importance":[131],"early":[133],"detection,":[134],"need":[137],"careful":[139],"management,":[141],"including":[142],"antibiotic":[143],"prophylaxis":[144],"before":[145],"invasive":[146],"procedures":[147],"associated":[148],"risk":[151],"bacteremia":[153],"in":[154],"patients":[155],"involvement.":[158]},"counts_by_year":[],"updated_date":"2026-11-09T13:22:03.289127","created_date":"2026-11-07T00:00:00"}