{"id":"https://openalex.org/W4415697384","doi":"https://doi.org/10.1186/s13023-025-04087-3","title":"Clinical manifestations and treatment of peripheral odontogenic keratocysts: two cases and a literature review","display_name":"Clinical manifestations and treatment of peripheral odontogenic keratocysts: two cases and a literature review","publication_year":2025,"publication_date":"2025-10-30","ids":{"openalex":"https://openalex.org/W4415697384","doi":"https://doi.org/10.1186/s13023-025-04087-3","pmid":"https://pubmed.ncbi.nlm.nih.gov/41168833","pmcid":"https://www.ncbi.nlm.nih.gov/pmc/articles/12573988"},"language":"en","primary_location":{"id":"doi:10.1186/s13023-025-04087-3","doi":"https://doi.org/10.1186/s13023-025-04087-3","is_oa":true,"landing_page_url":"https://doi.org/10.1186/s13023-025-04087-3","pdf_url":"https://ojrd.biomedcentral.com/counter/pdf/10.1186/s13023-025-04087-3","source":{"id":"https://openalex.org/S71291065","display_name":"Orphanet Journal of Rare Diseases","issn_l":"1750-1172","issn":["1750-1172"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["anvur-scientific","cwts-core","doaj","dongbi-b","doyens","jufo-1","ki-jl-1","medline","norway-1","oarl","poland-100","russia-white-list-2","vabb-shw"],"host_organization":"https://openalex.org/P4310320256","host_organization_name":"BioMed Central","host_organization_lineage":["https://openalex.org/P4310320256","https://openalex.org/P4310319965"],"host_organization_lineage_names":["BioMed Central","Springer Nature"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Orphanet Journal of Rare Diseases","raw_type":"journal-article"},"volume":null,"type":"article","indexed_in":["crossref","doaj","pubmed"],"open_access":{"is_oa":true,"oa_status":"gold","oa_url":"https://ojrd.biomedcentral.com/counter/pdf/10.1186/s13023-025-04087-3","any_repository_has_fulltext":true},"authorships":[{"author_position":"first","author":{"id":null,"display_name":"Yu Huang","orcid":null,"observed_orcids":[]},"institutions":[{"id":"https://openalex.org/I183519381","display_name":"Capital Medical University","ror":"https://ror.org/013xs5b60","country_code":"CN","type":"education","lineage":["https://openalex.org/I183519381"]}],"countries":["CN"],"is_corresponding":false,"raw_author_name":"Yu Huang","raw_affiliation_strings":["Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China","institution_ids":["https://openalex.org/I183519381"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5076856912","display_name":"Lirui Zhang","orcid":"https://orcid.org/0000-0001-5061-8405","observed_orcids":["https://orcid.org/0000-0001-5061-8405"]},"institutions":[{"id":"https://openalex.org/I183519381","display_name":"Capital Medical University","ror":"https://ror.org/013xs5b60","country_code":"CN","type":"education","lineage":["https://openalex.org/I183519381"]}],"countries":["CN"],"is_corresponding":false,"raw_author_name":"Lirui Zhang","raw_affiliation_strings":["Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China","institution_ids":["https://openalex.org/I183519381"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5101212120","display_name":"Xiaohong Yuan","orcid":"https://orcid.org/0000-0002-0429-7281","observed_orcids":["https://orcid.org/0000-0002-0429-7281"]},"institutions":[{"id":"https://openalex.org/I183519381","display_name":"Capital Medical University","ror":"https://ror.org/013xs5b60","country_code":"CN","type":"education","lineage":["https://openalex.org/I183519381"]}],"countries":["CN"],"is_corresponding":false,"raw_author_name":"Xiaohong Yuan","raw_affiliation_strings":["Department of Oral Pathology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, Beijing, 100070, China"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Oral Pathology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, Beijing, 100070, China","institution_ids":["https://openalex.org/I183519381"]}]},{"author_position":"last","author":{"id":"https://openalex.org/A5000190032","display_name":"Zhien Feng","orcid":"https://orcid.org/0000-0003-1952-6734","observed_orcids":["https://orcid.org/0000-0003-1952-6734"]},"institutions":[{"id":"https://openalex.org/I183519381","display_name":"Capital Medical University","ror":"https://ror.org/013xs5b60","country_code":"CN","type":"education","lineage":["https://openalex.org/I183519381"]}],"countries":["CN"],"is_corresponding":true,"raw_author_name":"Zhien Feng","raw_affiliation_strings":["Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China. jyfzhen@mail.ccmu.edu.cn","Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China"],"raw_orcid":"https://orcid.org/0000-0003-1952-6734","affiliations":[{"raw_affiliation_string":"Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China. jyfzhen@mail.ccmu.edu.cn","institution_ids":["https://openalex.org/I183519381"]},{"raw_affiliation_string":"Department of Oral and Maxillofacial-Head and Neck Oncology, Beijing Stomatological Hospital, Capital Medical University, No.9 Fanjiacun Road, FengTai District, 100070, Beijing, China","institution_ids":["https://openalex.org/I183519381"]}]}],"institutions":[],"countries_distinct_count":1,"institutions_distinct_count":1,"corresponding_author_ids":["https://openalex.org/A5000190032"],"corresponding_institution_ids":["https://openalex.org/I183519381"],"apc_list":{"value":2990,"currency":"USD","value_usd":2990},"apc_paid":{"value":2990,"currency":"USD","value_usd":2990},"fwci":0.9174,"has_fulltext":true,"cited_by_count":1,"citation_normalized_percentile":{"value":0.77867953,"is_in_top_1_percent":false,"is_in_top_10_percent":false},"cited_by_percentile_year":{"min":93,"max":96},"biblio":{"volume":"20","issue":"1","first_page":"550","last_page":"550"},"is_retracted":false,"is_paratext":false,"is_xpac":false,"primary_topic":{"id":"https://openalex.org/T11787","display_name":"Oral and Maxillofacial Pathology","score":1.0,"subfield":{"id":"https://openalex.org/subfields/3504","display_name":"Oral Surgery"},"field":{"id":"https://openalex.org/fields/35","display_name":"Dentistry"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},"topics":[{"id":"https://openalex.org/T11787","display_name":"Oral and Maxillofacial Pathology","score":1.0,"subfield":{"id":"https://openalex.org/subfields/3504","display_name":"Oral Surgery"},"field":{"id":"https://openalex.org/fields/35","display_name":"Dentistry"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},{"id":"https://openalex.org/T11919","display_name":"dental development and anomalies","score":0.0,"subfield":{"id":"https://openalex.org/subfields/1312","display_name":"Molecular Biology"},"field":{"id":"https://openalex.org/fields/13","display_name":"Biochemistry, Genetics and Molecular Biology"},"domain":{"id":"https://openalex.org/domains/1","display_name":"Life Sciences"}},{"id":"https://openalex.org/T12183","display_name":"Teratomas and Epidermoid Cysts","score":0.0,"subfield":{"id":"https://openalex.org/subfields/2746","display_name":"Surgery"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}}],"keywords":[{"id":"https://openalex.org/keywords/odontogenic-keratocyst","display_name":"odontogenic keratocyst","score":0.9869999885559082},{"id":"https://openalex.org/keywords/buccal-mucosa","display_name":"buccal mucosa","score":0.8519999980926514},{"id":"https://openalex.org/keywords/postoperative-recurrence","display_name":"postoperative recurrence","score":0.6690000295639038},{"id":"https://openalex.org/keywords/adhesion","display_name":"adhesion","score":0.5799999833106995},{"id":"https://openalex.org/keywords/soft-tissue-cyst","display_name":"soft tissue cyst","score":0.5329999923706055},{"id":"https://openalex.org/keywords/cyst-treatment","display_name":"cyst treatment","score":0.3179999887943268}],"concepts":[{"id":"https://openalex.org/C71924100","wikidata":"https://www.wikidata.org/wiki/Q11190","display_name":"Medicine","level":0,"score":0.7955999970436096},{"id":"https://openalex.org/C2778125672","wikidata":"https://www.wikidata.org/wiki/Q769266","display_name":"Odontogenic","level":2,"score":0.7105000019073486},{"id":"https://openalex.org/C16005928","wikidata":"https://www.wikidata.org/wiki/Q171171","display_name":"Dermatology","level":1,"score":0.5489000082015991},{"id":"https://openalex.org/C47042493","wikidata":"https://www.wikidata.org/wiki/Q265799","display_name":"Human genetics","level":3,"score":0.5439000129699707},{"id":"https://openalex.org/C46762472","wikidata":"https://www.wikidata.org/wiki/Q178648","display_name":"Peripheral","level":2,"score":0.40610000491142273},{"id":"https://openalex.org/C136948725","wikidata":"https://www.wikidata.org/wiki/Q1458306","display_name":"Soft tissue","level":2,"score":0.3797999918460846},{"id":"https://openalex.org/C142724271","wikidata":"https://www.wikidata.org/wiki/Q7208","display_name":"Pathology","level":1,"score":0.3517000079154968},{"id":"https://openalex.org/C2779134260","wikidata":"https://www.wikidata.org/wiki/Q12136","display_name":"Disease","level":2,"score":0.34619998931884766},{"id":"https://openalex.org/C2779473830","wikidata":"https://www.wikidata.org/wiki/Q1540899","display_name":"MEDLINE","level":2,"score":0.2985999882221222},{"id":"https://openalex.org/C141071460","wikidata":"https://www.wikidata.org/wiki/Q40821","display_name":"Surgery","level":1,"score":0.27649998664855957}],"mesh":[{"descriptor_ui":"D006801","descriptor_name":"Humans","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D009807","descriptor_name":"Odontogenic Cysts","qualifier_ui":"Q000175","qualifier_name":"diagnosis","is_major_topic":true},{"descriptor_ui":"D009807","descriptor_name":"Odontogenic Cysts","qualifier_ui":"Q000473","qualifier_name":"pathology","is_major_topic":true},{"descriptor_ui":"D009807","descriptor_name":"Odontogenic Cysts","qualifier_ui":"Q000601","qualifier_name":"surgery","is_major_topic":true}],"locations_count":4,"locations":[{"id":"doi:10.1186/s13023-025-04087-3","doi":"https://doi.org/10.1186/s13023-025-04087-3","is_oa":true,"landing_page_url":"https://doi.org/10.1186/s13023-025-04087-3","pdf_url":"https://ojrd.biomedcentral.com/counter/pdf/10.1186/s13023-025-04087-3","source":{"id":"https://openalex.org/S71291065","display_name":"Orphanet Journal of Rare Diseases","issn_l":"1750-1172","issn":["1750-1172"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["anvur-scientific","cwts-core","doaj","dongbi-b","doyens","jufo-1","ki-jl-1","medline","norway-1","oarl","poland-100","russia-white-list-2","vabb-shw"],"host_organization":"https://openalex.org/P4310320256","host_organization_name":"BioMed Central","host_organization_lineage":["https://openalex.org/P4310320256","https://openalex.org/P4310319965"],"host_organization_lineage_names":["BioMed Central","Springer Nature"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Orphanet Journal of Rare Diseases","raw_type":"journal-article"},{"id":"pmh:oai:europepmc.org:11383509","doi":null,"is_oa":true,"landing_page_url":"https://www.ncbi.nlm.nih.gov/pmc/articles/12573988","pdf_url":null,"source":{"id":"https://openalex.org/S4306400806","display_name":"Europe PMC (PubMed Central)","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1303153112","host_organization_name":"European Bioinformatics Institute","host_organization_lineage":["https://openalex.org/I1303153112"],"host_organization_lineage_names":[],"type":"repository"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":null,"raw_type":"Text"},{"id":"pmid:41168833","doi":null,"is_oa":false,"landing_page_url":"https://pubmed.ncbi.nlm.nih.gov/41168833","pdf_url":null,"source":{"id":"https://openalex.org/S4306525036","display_name":"PubMed","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Orphanet journal of rare diseases","raw_type":"Journal Article"},{"id":"pmh:oai:doaj.org/article:1ccd64bcbafb48a6a468b9982c2f0592","doi":null,"is_oa":true,"landing_page_url":"https://doaj.org/article/1ccd64bcbafb48a6a468b9982c2f0592","pdf_url":null,"source":{"id":"https://openalex.org/S4306401280","display_name":"DOAJ (DOAJ: Directory of Open Access Journals)","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":null,"host_organization_name":null,"host_organization_lineage":[],"host_organization_lineage_names":[],"type":"repository"},"license":"cc-by-sa","license_id":"https://openalex.org/licenses/cc-by-sa","version":"submittedVersion","is_accepted":false,"is_published":false,"raw_source_name":"Orphanet Journal of Rare Diseases, Vol 20, Iss 1, Pp 1-10 (2025)","raw_type":"article"}],"best_oa_location":{"id":"doi:10.1186/s13023-025-04087-3","doi":"https://doi.org/10.1186/s13023-025-04087-3","is_oa":true,"landing_page_url":"https://doi.org/10.1186/s13023-025-04087-3","pdf_url":"https://ojrd.biomedcentral.com/counter/pdf/10.1186/s13023-025-04087-3","source":{"id":"https://openalex.org/S71291065","display_name":"Orphanet Journal of Rare Diseases","issn_l":"1750-1172","issn":["1750-1172"],"is_oa":true,"is_in_doaj":true,"is_core":true,"listed_in":["anvur-scientific","cwts-core","doaj","dongbi-b","doyens","jufo-1","ki-jl-1","medline","norway-1","oarl","poland-100","russia-white-list-2","vabb-shw"],"host_organization":"https://openalex.org/P4310320256","host_organization_name":"BioMed Central","host_organization_lineage":["https://openalex.org/P4310320256","https://openalex.org/P4310319965"],"host_organization_lineage_names":["BioMed Central","Springer Nature"],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Orphanet Journal of Rare Diseases","raw_type":"journal-article"},"sustainable_development_goals":[{"score":0.98580002784729,"id":"https://metadata.un.org/sdg/3","display_name":"Good health and well-being"}],"study_designs":[],"awards":[{"id":"https://openalex.org/G7117006826","display_name":null,"funder_award_id":"20230484404","funder_id":"https://openalex.org/F4320334978","funder_display_name":"Beijing Nova Program"}],"funders":[{"id":"https://openalex.org/F4320334978","display_name":"Beijing Nova Program","ror":"https://ror.org/034k14f91"}],"has_content":{"grobid_xml":true,"pdf":true},"content_urls":{"pdf":"https://content.openalex.org/works/W4415697384.pdf","grobid_xml":"https://content.openalex.org/works/W4415697384.grobid-xml"},"referenced_works_count":48,"referenced_works":["https://openalex.org/W1991899482","https://openalex.org/W1994296415","https://openalex.org/W2000445514","https://openalex.org/W2005230466","https://openalex.org/W2013909627","https://openalex.org/W2019614148","https://openalex.org/W2024626035","https://openalex.org/W2025105891","https://openalex.org/W2035389541","https://openalex.org/W2037397547","https://openalex.org/W2041235422","https://openalex.org/W2042406792","https://openalex.org/W2043284516","https://openalex.org/W2043408474","https://openalex.org/W2048620667","https://openalex.org/W2052243760","https://openalex.org/W2053029363","https://openalex.org/W2076602355","https://openalex.org/W2090673299","https://openalex.org/W2104473553","https://openalex.org/W2105364566","https://openalex.org/W2108489687","https://openalex.org/W2109891715","https://openalex.org/W2135057618","https://openalex.org/W2140116135","https://openalex.org/W2142600325","https://openalex.org/W2165840527","https://openalex.org/W2170706202","https://openalex.org/W2195784869","https://openalex.org/W2561013000","https://openalex.org/W2728255407","https://openalex.org/W2902613096","https://openalex.org/W2912865555","https://openalex.org/W2946481695","https://openalex.org/W2955858289","https://openalex.org/W2956145264","https://openalex.org/W3090691882","https://openalex.org/W3095095958","https://openalex.org/W3133584151","https://openalex.org/W3135011746","https://openalex.org/W3161571846","https://openalex.org/W3191728288","https://openalex.org/W4213432903","https://openalex.org/W4324020770","https://openalex.org/W4365810927","https://openalex.org/W4380883051","https://openalex.org/W4402526500","https://openalex.org/W4405883665"],"related_works":["https://openalex.org/W4324335364","https://openalex.org/W4380883051","https://openalex.org/W3090691882","https://openalex.org/W7172499363","https://openalex.org/W4399447296","https://openalex.org/W4399440379","https://openalex.org/W4408243822","https://openalex.org/W3025418945","https://openalex.org/W2163941407","https://openalex.org/W3110926255"],"abstract_inverted_index":{"BACKGROUND:":[0],"Peripheral":[1],"odontogenic":[2,11],"keratocyst":[3,12],"(POKC)":[4],"is":[5],"a":[6,35],"rare":[7],"extraosseous":[8],"manifestation":[9],"of":[10,15,51,76,101,134],"(OKC).":[13],"Because":[14,113],"their":[16],"anatomical":[17],"locations,":[18],"OKCs":[19],"and":[20,68,74,94,126],"POKCs":[21,52,84,114],"necessitate":[22],"slightly":[23],"different":[24],"treatment":[25,73,133],"approaches.":[26],"However,":[27],"the":[28,54,65,70,77,91,95,102,118,132,136],"reported":[29,66],"literature":[30],"has":[31],"not":[32],"yet":[33],"reached":[34],"definitive":[36],"conclusion":[37],"on":[38],"this":[39,86],"matter.":[40],"METHODS:":[41],"This":[42],"study":[43],"included":[44],"2":[45],"patients":[46,82],"who":[47],"experienced":[48,88],"postoperative":[49],"recurrence":[50,89,109],"in":[53,85,117],"right":[55],"buccal":[56],"mucosa":[57],"from":[58],"2018":[59],"to":[60,124,129],"2020.":[61],"Additionally,":[62],"we":[63],"reviewed":[64],"cases":[67],"summarized":[69],"clinical":[71],"features,":[72],"prognosis":[75],"POKCs.":[78],"RESULTS:":[79],"The":[80],"two":[81],"with":[83,104],"report":[87],"after":[90],"first":[92],"surgery,":[93],"second":[96],"operation":[97],"involved":[98],"microscopic":[99],"excision":[100,144],"lesion":[103],"its":[105],"adherent":[106],"tissue.":[107],"No":[108],"was":[110],"observed.":[111],"CONCLUSIONS:":[112],"are":[115,122],"located":[116],"soft":[119],"tissue,":[120],"they":[121],"difficult":[123],"remove":[125],"therefore":[127],"prone":[128],"recur.":[130],"In":[131],"POKCs,":[135],"surrounding":[137],"adhesions":[138],"can":[139],"also":[140],"be":[141,146],"removed.":[142],"Microscopic":[143],"should":[145],"performed":[147],"as":[148],"well.":[149]},"counts_by_year":[{"year":2026,"cited_by_count":1}],"updated_date":"2026-10-31T12:09:11.096373","created_date":"2025-10-30T00:00:00"}
