{"id":"https://openalex.org/W4297239667","doi":"https://doi.org/10.3171/case22220","title":"Multiple-site neural tube defects complicated by multiple-site split cord malformations and thickened filum terminale: experience at a pediatric neurosurgical teaching hospital in Ethiopia. Illustrative case","display_name":"Multiple-site neural tube defects complicated by multiple-site split cord malformations and thickened filum terminale: experience at a pediatric neurosurgical teaching hospital in Ethiopia. Illustrative case","publication_year":2022,"publication_date":"2022-09-19","ids":{"openalex":"https://openalex.org/W4297239667","doi":"https://doi.org/10.3171/case22220","pmid":"https://pubmed.ncbi.nlm.nih.gov/36593675","pmcid":"https://www.ncbi.nlm.nih.gov/pmc/articles/9514283"},"language":"en","primary_location":{"id":"doi:10.3171/case22220","doi":"https://doi.org/10.3171/case22220","is_oa":true,"landing_page_url":"https://doi.org/10.3171/case22220","pdf_url":"https://thejns.org/downloadpdf/journals/j-neurosurg-case-lessons/4/12/article-CASE22220.pdf","source":{"id":"https://openalex.org/S4210221338","display_name":"Journal of Neurosurgery Case Lessons","issn_l":"2694-1902","issn":["2694-1902"],"is_oa":false,"is_in_doaj":false,"is_core":true,"listed_in":["cwts-core"],"host_organization":null,"host_organization_name":null,"host_organization_lineage":[],"host_organization_lineage_names":[],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Journal of Neurosurgery: Case Lessons","raw_type":"journal-article"},"volume":null,"type":"article","is_traditional":true,"indexed_in":["crossref","pubmed"],"open_access":{"is_oa":true,"oa_status":"hybrid","oa_url":"https://thejns.org/downloadpdf/journals/j-neurosurg-case-lessons/4/12/article-CASE22220.pdf","any_repository_has_fulltext":true},"authorships":[{"author_position":"first","author":{"id":"https://openalex.org/A5049809498","display_name":"Mestet Yibeltal Shiferaw","orcid":"https://orcid.org/0000-0001-5073-6946","observed_orcids":["https://orcid.org/0000-0001-5073-6946"]},"institutions":[{"id":"https://openalex.org/I4537092","display_name":"Addis Ababa University","ror":"https://ror.org/038b8e254","country_code":"ET","type":"education","lineage":["https://openalex.org/I4537092"]}],"countries":["ET"],"is_corresponding":true,"raw_author_name":"Mestet Yibeltal Shiferaw","raw_affiliation_strings":["Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","Addis Ababa University, Ethiopia"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]},{"raw_affiliation_string":"Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5001788181","display_name":"Yemisirach Bizuneh Akililu","orcid":"https://orcid.org/0000-0001-9132-4331","observed_orcids":["https://orcid.org/0000-0001-9132-4331"]},"institutions":[{"id":"https://openalex.org/I4537092","display_name":"Addis Ababa University","ror":"https://ror.org/038b8e254","country_code":"ET","type":"education","lineage":["https://openalex.org/I4537092"]}],"countries":["ET"],"is_corresponding":false,"raw_author_name":"Yemisirach Bizuneh Akililu","raw_affiliation_strings":["Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","Addis Ababa University, Ethiopia"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]},{"raw_affiliation_string":"Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5103247125","display_name":"Bethelhem Yishak Worku","orcid":"https://orcid.org/0000-0001-8656-6379","observed_orcids":["https://orcid.org/0000-0001-8656-6379"]},"institutions":[{"id":"https://openalex.org/I4537092","display_name":"Addis Ababa University","ror":"https://ror.org/038b8e254","country_code":"ET","type":"education","lineage":["https://openalex.org/I4537092"]}],"countries":["ET"],"is_corresponding":false,"raw_author_name":"Bethelehem Yesehak Worku","raw_affiliation_strings":["Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","Addis Ababa University, Ethiopia"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]},{"raw_affiliation_string":"Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5062814006","display_name":"Tsegazeab Laeke T Mariam","orcid":null,"observed_orcids":[]},"institutions":[{"id":"https://openalex.org/I4537092","display_name":"Addis Ababa University","ror":"https://ror.org/038b8e254","country_code":"ET","type":"education","lineage":["https://openalex.org/I4537092"]}],"countries":["ET"],"is_corresponding":false,"raw_author_name":"Tsegazeab Laeke T/Mariam","raw_affiliation_strings":["Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","Addis Ababa University, Ethiopia"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]},{"raw_affiliation_string":"Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]}]},{"author_position":"last","author":{"id":"https://openalex.org/A5089947362","display_name":"Abenezer Tirsit","orcid":"https://orcid.org/0000-0002-0394-0343","observed_orcids":["https://orcid.org/0000-0002-0394-0343"]},"institutions":[{"id":"https://openalex.org/I4537092","display_name":"Addis Ababa University","ror":"https://ror.org/038b8e254","country_code":"ET","type":"education","lineage":["https://openalex.org/I4537092"]}],"countries":["ET"],"is_corresponding":false,"raw_author_name":"Abenezer Tirsit Aklilu","raw_affiliation_strings":["Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","Addis Ababa University, Ethiopia"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Department of Surgery, Neurosurgery Unit, Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]},{"raw_affiliation_string":"Addis Ababa University, Ethiopia","institution_ids":["https://openalex.org/I4537092"]}]}],"institutions":[],"countries_distinct_count":1,"institutions_distinct_count":1,"corresponding_author_ids":["https://openalex.org/A5049809498"],"corresponding_institution_ids":["https://openalex.org/I4537092"],"apc_list":null,"apc_paid":null,"fwci":0.1365,"has_fulltext":true,"cited_by_count":1,"citation_normalized_percentile":{"value":0.36611671,"is_in_top_1_percent":false,"is_in_top_10_percent":false},"cited_by_percentile_year":{"min":87,"max":93},"biblio":{"volume":"4","issue":"12","first_page":null,"last_page":null},"is_retracted":false,"is_paratext":false,"is_xpac":false,"primary_topic":{"id":"https://openalex.org/T11833","display_name":"Spinal Dysraphism and Malformations","score":1.0,"subfield":{"id":"https://openalex.org/subfields/2728","display_name":"Clinical Neurology"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},"topics":[{"id":"https://openalex.org/T11833","display_name":"Spinal Dysraphism and Malformations","score":1.0,"subfield":{"id":"https://openalex.org/subfields/2728","display_name":"Clinical Neurology"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},{"id":"https://openalex.org/T12716","display_name":"Congenital Anomalies and Fetal Surgery","score":9.999999747378752e-05,"subfield":{"id":"https://openalex.org/subfields/2746","display_name":"Surgery"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}},{"id":"https://openalex.org/T11030","display_name":"Scoliosis diagnosis and treatment","score":0.0,"subfield":{"id":"https://openalex.org/subfields/2746","display_name":"Surgery"},"field":{"id":"https://openalex.org/fields/27","display_name":"Medicine"},"domain":{"id":"https://openalex.org/domains/4","display_name":"Health Sciences"}}],"keywords":[{"id":"https://openalex.org/keywords/thoracic-meningocele","display_name":"thoracic meningocele","score":0.9070000052452087},{"id":"https://openalex.org/keywords/resource-limited-settings","display_name":"resource-limited settings","score":0.7630000114440918},{"id":"https://openalex.org/keywords/congenital-spinal-anomalies","display_name":"congenital spinal malformation","score":0.6290000081062317},{"id":"https://openalex.org/keywords/intraoperative-diagnosis","display_name":"intraoperative diagnosis","score":0.5149999856948853}],"concepts":[{"id":"https://openalex.org/C2778991078","wikidata":"https://www.wikidata.org/wiki/Q1362202","display_name":"Filum terminale","level":3,"score":0.9680917859077454},{"id":"https://openalex.org/C71924100","wikidata":"https://www.wikidata.org/wiki/Q11190","display_name":"Medicine","level":0,"score":0.935725212097168},{"id":"https://openalex.org/C2780594696","wikidata":"https://www.wikidata.org/wiki/Q1127402","display_name":"Neural tube","level":3,"score":0.744485080242157},{"id":"https://openalex.org/C2778478650","wikidata":"https://www.wikidata.org/wiki/Q844717","display_name":"Spina bifida","level":2,"score":0.503828227519989},{"id":"https://openalex.org/C2777003008","wikidata":"https://www.wikidata.org/wiki/Q548213","display_name":"Neural tube defect","level":4,"score":0.5022332668304443},{"id":"https://openalex.org/C2780775167","wikidata":"https://www.wikidata.org/wiki/Q9606","display_name":"Spinal cord","level":2,"score":0.49990344047546387},{"id":"https://openalex.org/C141071460","wikidata":"https://www.wikidata.org/wiki/Q40821","display_name":"Surgery","level":1,"score":0.4583839774131775},{"id":"https://openalex.org/C105702510","wikidata":"https://www.wikidata.org/wiki/Q514","display_name":"Anatomy","level":1,"score":0.3274977505207062},{"id":"https://openalex.org/C118552586","wikidata":"https://www.wikidata.org/wiki/Q7867","display_name":"Psychiatry","level":1,"score":0.0},{"id":"https://openalex.org/C95444343","wikidata":"https://www.wikidata.org/wiki/Q7141","display_name":"Cell biology","level":1,"score":0.0},{"id":"https://openalex.org/C196843134","wikidata":"https://www.wikidata.org/wiki/Q33196","display_name":"Embryo","level":2,"score":0.0},{"id":"https://openalex.org/C86803240","wikidata":"https://www.wikidata.org/wiki/Q420","display_name":"Biology","level":0,"score":0.0}],"mesh":[],"locations_count":3,"locations":[{"id":"doi:10.3171/case22220","doi":"https://doi.org/10.3171/case22220","is_oa":true,"landing_page_url":"https://doi.org/10.3171/case22220","pdf_url":"https://thejns.org/downloadpdf/journals/j-neurosurg-case-lessons/4/12/article-CASE22220.pdf","source":{"id":"https://openalex.org/S4210221338","display_name":"Journal of Neurosurgery Case Lessons","issn_l":"2694-1902","issn":["2694-1902"],"is_oa":false,"is_in_doaj":false,"is_core":true,"listed_in":["cwts-core"],"host_organization":null,"host_organization_name":null,"host_organization_lineage":[],"host_organization_lineage_names":[],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Journal of Neurosurgery: Case Lessons","raw_type":"journal-article"},{"id":"pmid:36593675","doi":null,"is_oa":false,"landing_page_url":"https://pubmed.ncbi.nlm.nih.gov/36593675","pdf_url":null,"source":{"id":"https://openalex.org/S4306525036","display_name":"PubMed","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Journal of neurosurgery. Case lessons","raw_type":"Journal Article"},{"id":"pmh:oai:pubmedcentral.nih.gov:9514283","doi":null,"is_oa":true,"landing_page_url":"https://pmc.ncbi.nlm.nih.gov/articles/PMC9514283/","pdf_url":null,"source":{"id":"https://openalex.org/S2764455111","display_name":"PubMed Central","issn_l":null,"issn":null,"is_oa":true,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":"cc-by-nc-nd","license_id":"https://openalex.org/licenses/cc-by-nc-nd","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"J Neurosurg Case Lessons","raw_type":"Text"}],"best_oa_location":{"id":"doi:10.3171/case22220","doi":"https://doi.org/10.3171/case22220","is_oa":true,"landing_page_url":"https://doi.org/10.3171/case22220","pdf_url":"https://thejns.org/downloadpdf/journals/j-neurosurg-case-lessons/4/12/article-CASE22220.pdf","source":{"id":"https://openalex.org/S4210221338","display_name":"Journal of Neurosurgery Case Lessons","issn_l":"2694-1902","issn":["2694-1902"],"is_oa":false,"is_in_doaj":false,"is_core":true,"listed_in":["cwts-core"],"host_organization":null,"host_organization_name":null,"host_organization_lineage":[],"host_organization_lineage_names":[],"type":"journal"},"license":"cc-by","license_id":"https://openalex.org/licenses/cc-by","version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Journal of Neurosurgery: Case Lessons","raw_type":"journal-article"},"sustainable_development_goals":[{"score":0.9537000060081482,"display_name":"Good health and well-being","id":"https://metadata.un.org/sdg/3"}],"study_designs":[{"display_name":"Case Report","id":"https://openalex.org/study-designs/case-report"}],"awards":[],"funders":[],"has_content":{"pdf":true,"grobid_xml":true},"content_urls":{"pdf":"https://content.openalex.org/works/W4297239667.pdf","grobid_xml":"https://content.openalex.org/works/W4297239667.grobid-xml"},"referenced_works_count":19,"referenced_works":["https://openalex.org/W209865686","https://openalex.org/W762164871","https://openalex.org/W1969736597","https://openalex.org/W1979032922","https://openalex.org/W2000615205","https://openalex.org/W2031525337","https://openalex.org/W2031887159","https://openalex.org/W2052431174","https://openalex.org/W2056248260","https://openalex.org/W2070237945","https://openalex.org/W2073935026","https://openalex.org/W2075380322","https://openalex.org/W2085784496","https://openalex.org/W2118311923","https://openalex.org/W2160784432","https://openalex.org/W2328981861","https://openalex.org/W2978153587","https://openalex.org/W3004923206","https://openalex.org/W3194772666"],"related_works":["https://openalex.org/W2978153587","https://openalex.org/W2031887159","https://openalex.org/W2031525337","https://openalex.org/W2004096855","https://openalex.org/W2085784496","https://openalex.org/W2158594212","https://openalex.org/W2160784432","https://openalex.org/W4386227029","https://openalex.org/W4366451075","https://openalex.org/W3194772666"],"abstract_inverted_index":{"BACKGROUND:":[0],"Multiple-site":[1],"open":[2],"neural":[3,30,46],"tube":[4,31],"defects":[5],"(MNTDs)":[6],"and":[7,34,57,84,98,101,130,174,187,200],"multiple-site":[8],"split":[9,35],"cord":[10,36],"malformations":[11],"(MSCMs)":[12],"are":[13,19],"extremely":[14],"rare":[15],"congenital":[16],"anomalies":[17],"that":[18],"defined":[20],"by":[21],"the":[22,53,65,153,166,170,175,180],"simultaneous":[23],"noncontiguous":[24],"occurrence":[25],"of":[26,55,80,92,96,116,132,165,172,191],"more":[27],"than":[28],"one":[29],"defect":[32],"(NTD)":[33],"malformation":[37],"(SCM),":[38],"respectively,":[39],"in":[40,48,64,138],"a":[41,72,77,108,156,163],"single":[42,195],"case":[43],"with":[44,76,107,122],"normal":[45],"tissue":[47],"between.":[49],"This":[50],"work":[51],"shows":[52],"cooccurrence":[54],"MNTDs":[56,81,154,192],"MSCMs,":[58],"which":[59],"has":[60],"never":[61],"been":[62],"reported":[63],"literature.":[66],"OBSERVATIONS:":[67],"A":[68],"single-stage":[69],"repair":[70,152],"for":[71,127,179],"13-day-old":[73],"female":[74],"neonate":[75],"preoperative":[78,123,142],"diagnosis":[79,91],"(thoracic":[82],"meningocele":[83],"thoracolumbar":[85,99],"myelomeningocele)":[86],"plus":[87],"an":[88],"additional":[89],"intraoperative":[90,117],"MSCMs":[93],"(type":[94],"3c)":[95],"thoracic":[97],"spine,":[100],"thickened":[102],"filum":[103],"terminale":[104],"was":[105],"done":[106],"favorable":[109],"smooth":[110],"postoperative":[111],"course.":[112],"LESSONS:":[113],"The":[114,183],"use":[115],"meticulous":[118],"surgical":[119],"technique":[120],"along":[121],"skin":[124],"stigmata":[125],"helped":[126],"anticipation,":[128],"detection,":[129],"treatment":[131],"associated":[133],"complex":[134],"spinal":[135],"MNTDs,":[136],"especially":[137],"resource-limited":[139],"settings,":[140],"where":[141],"magnetic":[143],"resonance":[144],"imaging":[145],"is":[146,161,197],"not":[147],"routinely":[148],"used.":[149],"Whether":[150],"to":[151,169,194],"as":[155],"single-":[157],"versus":[158],"multiple-stage":[159],"procedure":[160],"mainly":[162],"function":[164],"patient's":[167,181],"tolerance":[168],"duration":[171],"anesthesia":[173],"anticipated":[176],"blood":[177],"loss":[178],"age.":[182],"overall":[184],"developmental":[185],"biology":[186],"long-term":[188],"clinical":[189],"outcome":[190],"compared":[193],"NTD/SCM":[196],"poorly":[198],"understood":[199],"needs":[201],"further":[202],"study.":[203]},"counts_by_year":[{"year":2023,"cited_by_count":1}],"updated_date":"2026-11-10T11:39:43.021295","created_date":"2022-09-28T00:00:00"}
