{"id":"https://openalex.org/W1989333286","doi":"https://doi.org/10.1007/s12026-014-8485-4","title":"An analysis and decision tool to measure cost benefit of newborn screening for severe combined immunodeficiency (SCID) and related T-cell lymphopenia","display_name":"An analysis and decision tool to measure cost benefit of newborn screening for severe combined immunodeficiency (SCID) and related T-cell lymphopenia","publication_year":2014,"publication_date":"2014-03-05","ids":{"openalex":"https://openalex.org/W1989333286","doi":"https://doi.org/10.1007/s12026-014-8485-4","mag":"1989333286","pmid":"https://pubmed.ncbi.nlm.nih.gov/24599744"},"language":"en","primary_location":{"id":"doi:10.1007/s12026-014-8485-4","doi":"https://doi.org/10.1007/s12026-014-8485-4","is_oa":false,"landing_page_url":"https://doi.org/10.1007/s12026-014-8485-4","pdf_url":null,"source":{"id":"https://openalex.org/S70378559","display_name":"Immunologic Research","issn_l":"0257-277X","issn":["0257-277X","1559-0755"],"is_oa":false,"is_in_doaj":false,"is_core":true,"listed_in":["cwts-core","dongbi-d","doyens","jufo-1","ki-jl-1","medline","norway-1","poland-100","russia-white-list-2","vabb-shw"],"host_organization":"https://openalex.org/P4310319900","host_organization_name":"Springer Science+Business Media","host_organization_lineage":["https://openalex.org/P4310319900","https://openalex.org/P4310319965"],"host_organization_lineage_names":["Springer Science+Business Media","Springer Nature"],"type":"journal"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Immunologic Research","raw_type":"journal-article"},"volume":null,"type":"article","is_traditional":true,"indexed_in":["crossref","pubmed"],"open_access":{"is_oa":false,"oa_status":"closed","oa_url":null,"any_repository_has_fulltext":false},"authorships":[{"author_position":"first","author":{"id":"https://openalex.org/A5112195323","display_name":"Vicki Modell","orcid":"https://orcid.org/0000-0002-3764-0242","observed_orcids":["https://orcid.org/0000-0002-3764-0242"]},"institutions":[{"id":"https://openalex.org/I4210151911","display_name":"Jeffrey Modell Foundation","ror":"https://ror.org/04cc1bd73","country_code":"US","type":"nonprofit","lineage":["https://openalex.org/I4210151911"]}],"countries":["US"],"is_corresponding":false,"raw_author_name":"Vicki Modell","raw_affiliation_strings":["Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","Jeffrey Modell Foundation, New York, USA"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","institution_ids":["https://openalex.org/I4210151911"]},{"raw_affiliation_string":"Jeffrey Modell Foundation, New York, USA","institution_ids":["https://openalex.org/I4210151911"]}]},{"author_position":"middle","author":{"id":"https://openalex.org/A5041982688","display_name":"Megan Knaus","orcid":null,"observed_orcids":[]},"institutions":[{"id":"https://openalex.org/I4210151911","display_name":"Jeffrey Modell Foundation","ror":"https://ror.org/04cc1bd73","country_code":"US","type":"nonprofit","lineage":["https://openalex.org/I4210151911"]}],"countries":["US"],"is_corresponding":false,"raw_author_name":"Megan Knaus","raw_affiliation_strings":["Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","Jeffrey Modell Foundation, New York, USA"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","institution_ids":["https://openalex.org/I4210151911"]},{"raw_affiliation_string":"Jeffrey Modell Foundation, New York, USA","institution_ids":["https://openalex.org/I4210151911"]}]},{"author_position":"last","author":{"id":"https://openalex.org/A5112467439","display_name":"Fred Modell","orcid":"https://orcid.org/0000-0002-3764-0242","observed_orcids":["https://orcid.org/0000-0002-3764-0242"]},"institutions":[{"id":"https://openalex.org/I4210151911","display_name":"Jeffrey Modell Foundation","ror":"https://ror.org/04cc1bd73","country_code":"US","type":"nonprofit","lineage":["https://openalex.org/I4210151911"]}],"countries":["US"],"is_corresponding":true,"raw_author_name":"Fred Modell","raw_affiliation_strings":["Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","Jeffrey Modell Foundation, New York, USA"],"raw_orcid":null,"affiliations":[{"raw_affiliation_string":"Jeffrey Modell Foundation, 780 Third Avenue, 47th Floor, New York, NY, 10017, USA","institution_ids":["https://openalex.org/I4210151911"]},{"raw_affiliation_string":"Jeffrey Modell Foundation, New York, USA","institution_ids":["https://openalex.org/I4210151911"]}]}],"institutions":[],"countries_distinct_count":1,"institutions_distinct_count":1,"corresponding_author_ids":["https://openalex.org/A5112467439"],"corresponding_institution_ids":["https://openalex.org/I4210151911"],"apc_list":{"value":2890,"currency":"USD","value_usd":2890},"apc_paid":null,"fwci":2.9212,"has_fulltext":false,"cited_by_count":52,"citation_normalized_percentile":{"value":0.91463235,"is_in_top_1_percent":false,"is_in_top_10_percent":true},"cited_by_percentile_year":{"min":87,"max":99},"biblio":{"volume":"60","issue":"1","first_page":"145","last_page":"152"},"is_retracted":false,"is_paratext":false,"is_xpac":false,"primary_topic":{"id":"https://openalex.org/T11725","display_name":"Immunodeficiency and Autoimmune Disorders","score":0.9940999746322632,"subfield":{"id":"https://openalex.org/subfields/2403","display_name":"Immunology"},"field":{"id":"https://openalex.org/fields/24","display_name":"Immunology and Microbiology"},"domain":{"id":"https://openalex.org/domains/1","display_name":"Life Sciences"}},"topics":[{"id":"https://openalex.org/T11725","display_name":"Immunodeficiency and Autoimmune Disorders","score":0.9940999746322632,"subfield":{"id":"https://openalex.org/subfields/2403","display_name":"Immunology"},"field":{"id":"https://openalex.org/fields/24","display_name":"Immunology and Microbiology"},"domain":{"id":"https://openalex.org/domains/1","display_name":"Life Sciences"}},{"id":"https://openalex.org/T10804","display_name":"Health Systems, Economic Evaluations, Quality of Life","score":0.0015999999595806003,"subfield":{"id":"https://openalex.org/subfields/2002","display_name":"Economics and Econometrics"},"field":{"id":"https://openalex.org/fields/20","display_name":"Economics, Econometrics and Finance"},"domain":{"id":"https://openalex.org/domains/2","display_name":"Social Sciences"}},{"id":"https://openalex.org/T11027","display_name":"Metabolism and Genetic Disorders","score":0.0003000000142492354,"subfield":{"id":"https://openalex.org/subfields/1308","display_name":"Clinical Biochemistry"},"field":{"id":"https://openalex.org/fields/13","display_name":"Biochemistry, Genetics and Molecular Biology"},"domain":{"id":"https://openalex.org/domains/1","display_name":"Life Sciences"}}],"keywords":[{"id":"https://openalex.org/keywords/severe-combined-immunodeficiency","display_name":"severe combined immunodeficiency","score":0.9860000014305115},{"id":"https://openalex.org/keywords/newborn-screening","display_name":"newborn screening","score":0.8799999952316284},{"id":"https://openalex.org/keywords/t-cell-lymphopenia","display_name":"T-cell lymphopenia","score":0.9779999852180481},{"id":"https://openalex.org/keywords/cost-benefit-analysis","display_name":"cost-benefit analysis","score":0.8610000014305115},{"id":"https://openalex.org/keywords/t-cell-receptor-excision-circles","display_name":"TREC","score":0.8840000033378601},{"id":"https://openalex.org/keywords/decision-tree","display_name":"decision tree","score":0.7059999704360962},{"id":"https://openalex.org/keywords/screening-thresholds","display_name":"screening thresholds","score":0.5059999823570251},{"id":"https://openalex.org/keywords/economic-impact","display_name":"economic impact","score":0.7580000162124634},{"id":"https://openalex.org/keywords/public-health-decision-making","display_name":"public health decision-making","score":0.5270000100135803}],"concepts":[{"id":"https://openalex.org/C2779468541","wikidata":"https://www.wikidata.org/wiki/Q1334408","display_name":"Severe combined immunodeficiency","level":3,"score":0.7144513726234436},{"id":"https://openalex.org/C2776169613","wikidata":"https://www.wikidata.org/wiki/Q2305910","display_name":"Newborn screening","level":2,"score":0.6303185224533081},{"id":"https://openalex.org/C2908647359","wikidata":"https://www.wikidata.org/wiki/Q2625603","display_name":"Population","level":2,"score":0.5437227487564087},{"id":"https://openalex.org/C71924100","wikidata":"https://www.wikidata.org/wiki/Q11190","display_name":"Medicine","level":0,"score":0.5361193418502808},{"id":"https://openalex.org/C138816342","wikidata":"https://www.wikidata.org/wiki/Q189603","display_name":"Public health","level":2,"score":0.48945677280426025},{"id":"https://openalex.org/C61511704","wikidata":"https://www.wikidata.org/wiki/Q1671857","display_name":"Incidence (geometry)","level":2,"score":0.4891100525856018},{"id":"https://openalex.org/C187212893","wikidata":"https://www.wikidata.org/wiki/Q123028","display_name":"Pediatrics","level":1,"score":0.4028836786746979},{"id":"https://openalex.org/C203014093","wikidata":"https://www.wikidata.org/wiki/Q101929","display_name":"Immunology","level":1,"score":0.40202203392982483},{"id":"https://openalex.org/C99454951","wikidata":"https://www.wikidata.org/wiki/Q932068","display_name":"Environmental health","level":1,"score":0.22457832098007202},{"id":"https://openalex.org/C86803240","wikidata":"https://www.wikidata.org/wiki/Q420","display_name":"Biology","level":0,"score":0.1656838059425354},{"id":"https://openalex.org/C142724271","wikidata":"https://www.wikidata.org/wiki/Q7208","display_name":"Pathology","level":1,"score":0.12676012516021729},{"id":"https://openalex.org/C120665830","wikidata":"https://www.wikidata.org/wiki/Q14620","display_name":"Optics","level":1,"score":0.0},{"id":"https://openalex.org/C104317684","wikidata":"https://www.wikidata.org/wiki/Q7187","display_name":"Gene","level":2,"score":0.0},{"id":"https://openalex.org/C55493867","wikidata":"https://www.wikidata.org/wiki/Q7094","display_name":"Biochemistry","level":1,"score":0.0},{"id":"https://openalex.org/C121332964","wikidata":"https://www.wikidata.org/wiki/Q413","display_name":"Physics","level":0,"score":0.0}],"mesh":[{"descriptor_ui":"D003362","descriptor_name":"Cost-Benefit Analysis","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D003661","descriptor_name":"Decision Support Techniques","qualifier_ui":null,"qualifier_name":null,"is_major_topic":true},{"descriptor_ui":"D006801","descriptor_name":"Humans","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D007231","descriptor_name":"Infant, Newborn","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D008231","descriptor_name":"Lymphopenia","qualifier_ui":"Q000175","qualifier_name":"diagnosis","is_major_topic":true},{"descriptor_ui":"D013601","descriptor_name":"T-Lymphocytes","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D014481","descriptor_name":"United States","qualifier_ui":null,"qualifier_name":null,"is_major_topic":false},{"descriptor_ui":"D015997","descriptor_name":"Neonatal Screening","qualifier_ui":"Q000191","qualifier_name":"economics","is_major_topic":true},{"descriptor_ui":"D016511","descriptor_name":"Severe Combined Immunodeficiency","qualifier_ui":"Q000175","qualifier_name":"diagnosis","is_major_topic":true}],"locations_count":2,"locations":[{"id":"doi:10.1007/s12026-014-8485-4","doi":"https://doi.org/10.1007/s12026-014-8485-4","is_oa":false,"landing_page_url":"https://doi.org/10.1007/s12026-014-8485-4","pdf_url":null,"source":{"id":"https://openalex.org/S70378559","display_name":"Immunologic Research","issn_l":"0257-277X","issn":["0257-277X","1559-0755"],"is_oa":false,"is_in_doaj":false,"is_core":true,"listed_in":["cwts-core","dongbi-d","doyens","jufo-1","ki-jl-1","medline","norway-1","poland-100","russia-white-list-2","vabb-shw"],"host_organization":"https://openalex.org/P4310319900","host_organization_name":"Springer Science+Business Media","host_organization_lineage":["https://openalex.org/P4310319900","https://openalex.org/P4310319965"],"host_organization_lineage_names":["Springer Science+Business Media","Springer Nature"],"type":"journal"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Immunologic Research","raw_type":"journal-article"},{"id":"pmid:24599744","doi":null,"is_oa":false,"landing_page_url":"https://pubmed.ncbi.nlm.nih.gov/24599744","pdf_url":null,"source":{"id":"https://openalex.org/S4306525036","display_name":"PubMed","issn_l":null,"issn":null,"is_oa":false,"is_in_doaj":false,"is_core":false,"listed_in":[],"host_organization":"https://openalex.org/I1299303238","host_organization_name":"National Institutes of Health","host_organization_lineage":["https://openalex.org/I1299303238"],"host_organization_lineage_names":[],"type":"repository"},"license":null,"license_id":null,"version":"publishedVersion","is_accepted":true,"is_published":true,"raw_source_name":"Immunologic research","raw_type":"Journal Article"}],"best_oa_location":null,"sustainable_development_goals":[{"score":0.9763000011444092,"id":"https://metadata.un.org/sdg/3","display_name":"Good health and well-being"}],"study_designs":[],"awards":[],"funders":[],"has_content":{"pdf":false,"grobid_xml":false},"content_urls":null,"referenced_works_count":14,"referenced_works":["https://openalex.org/W1974476439","https://openalex.org/W1978660935","https://openalex.org/W1988957385","https://openalex.org/W2005419283","https://openalex.org/W2008298347","https://openalex.org/W2027008928","https://openalex.org/W2048279530","https://openalex.org/W2058847134","https://openalex.org/W2060862586","https://openalex.org/W2067051399","https://openalex.org/W2096164159","https://openalex.org/W2108676766","https://openalex.org/W2152461163","https://openalex.org/W2330288813"],"related_works":["https://openalex.org/W2930019001","https://openalex.org/W3134308679","https://openalex.org/W1815961251","https://openalex.org/W3009899890","https://openalex.org/W2915353766","https://openalex.org/W2074334845","https://openalex.org/W2971019661","https://openalex.org/W3201922747","https://openalex.org/W2034704801","https://openalex.org/W4390126064"],"abstract_inverted_index":null,"counts_by_year":[{"year":2026,"cited_by_count":4},{"year":2025,"cited_by_count":1},{"year":2024,"cited_by_count":3},{"year":2023,"cited_by_count":1},{"year":2022,"cited_by_count":2},{"year":2021,"cited_by_count":4},{"year":2020,"cited_by_count":4},{"year":2019,"cited_by_count":8},{"year":2018,"cited_by_count":3},{"year":2017,"cited_by_count":5},{"year":2016,"cited_by_count":2},{"year":2015,"cited_by_count":8},{"year":2014,"cited_by_count":7}],"updated_date":"2026-11-04T10:54:05.112534","created_date":"2016-06-24T00:00:00"}
